Glossary in Congenital Malformations

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General:

#Camptodactyly: Means permenant flexion of one or more fingers. (Campto- means flex).

#Cavum septi pellucidi and cavum Vergae: As the corpus callosum grows, the banks of the median groove ventral to the callosum separate to form a small pocket that develops into the cavum septum pellucidi (also kown as 5th ventricle), a space that persists until term and that gradually narrows to a potential space in the adult. Persistence of the cavum septi pellucidi, and its posterior extension the cavum vergae are not malformations. The cavum septi pellucidi and cavum vergae should not be communicating with the ventricles.

#Cephalocele (encephalocele): a herniation of cranial contents through a skull defect.

#Cerebellar dysplasia: I prefer to limit this term to abnormal formation of the cerebellar gyri and/or dentate nuclei in order to distinguish this entity from cerebellar heterotopia. The hemispheres are preferentially affected.

#Cerebellar Dysplasia: [according to Rorke et al., 1968]

·         Compact groups of mature neurons: Can be found in 58% of normal fetus, according to Rorke et al.

·         Focal and perivascular immature granular cell collections: They are nests of primitive looking cells that frequently arrange around blood vessels. They are found in about 25% of all cases but they should not be seen after the 4th postnatal month.

·         Heterotaxias: Poorly organized mixed cell rests.

·         Heterotopias: Well-organized cell rests composed of all components of cerebellar arrayed in normal relationships. Heterotopias are much less common than heterotaxias.

·         Heterotopias and heterotaxias are associated with trisomy 13 and to a lesser extent trisomy 18. They are also associated with encephalocele.

#Cerebellar hemispheric (lateral) aplasia or hypoplasia: Uncommon and often associated with other anomalies. Complete absence of cerebellar tissue is extremely rare. Hemiagenesis is less rare and is usually associated with an atrophy of the inferior cerebellar peduncle and contralateral inferior olive. It may be asymptomatic, even in adulthood. In the hypoplastic cases, the cerebellar sulci displayed areas devoided of neuronal cells and formed by gliotic tissue. There is also corresponding reduction in number of neurons in the pontine nuclei. According to Norman et al., hypoplasias of the whole cerebellum, in a sense that the whole cerebellum is grossly small and the internal and external granule cells and Purkinje cells appear normal, are virtually nonexistent. Pathologically, it is very difficult to separate hypoplasia and degeneration. Most of the reported cases of hypoplasias are proved to be degenerative.

#Chiari Malformations: Cerebellar deformity associated with hydrocephalus.

·         Type I:

Clinical: Often asymptomatic but may also cause headache, neck pain, and apneoic episodes and near-miss sudden death syndrome. Adults may have cerebellar ataxia, neck pain, pyramidal syndrome, or dissociated sensory loss indicative of syringomyelia.

Pathology: Conical elongations of the tonsils and neighbouring parts of the cerebellar hemispheres extend into the vertebral canal (i.e., below the foramen of magnum). The protruded cerebellar tissue could be histologically normal, infracted or sclerosed. The medulla is either unaffected or flattened by the cerebellar tongues. Often associated with syringomyelia (50%), hydromyelia and syringomyelia, (50%) and hydrocephalus (10%). Chiari malformations have four subgroups:

·         Subgroup I: present in childhood with hydrocephalus.

·         Subgroup II: associated with anomalies including occipitalization of the atlas, Klippel-Feil anomalies, other abnormalies of C1 and C2, and sometimes large tonsils.

·         Subgroup III: acquired deformities of the foramen magnum such as basilar impression, often have associated syringomyelia.

·         Subgroup IV: tonsilla ectopia, myelomeningoceles, and other abnormalities as fenestration of the falx and dysgenesis of the corpus callosum.

·         Type II: Displacement of the cerebellar vermis combined with deformities of the medulla and tectal plate. Often associated with syringomyelia, hydromyelia, spinal bifida, meningocele, and hydrocephalus. It can also associate with other malformation of the brain, cranium and meninges, cardiovascular, gastrointestinal and genitourinary systems. Chiari type II malformation is probably secondary to a neural tube defect. All Chiar II malformations initially described has neural tube defects and the term “Chiari II” malformation should be limited to those cases with neural tube defects.

·         Arnold-Chiari Syndrome: Chiari type II malformation associated with meningocele.

·         Type III: Encephalocele formed by herniation of the structures of the posterior fossa, including the cerebellum, through an occipitocervical or high cervical bony defect. There may also be beaking of of the tectum, elongation and kinging of the brain astem and lumbar spina bifida.

·         Type IV: Hypoplastic cerebellum. (This term is not used anymore).

#Choristoma: Non-neoplastic, tumor-like masses of histologically normal tissue in an abnormal location. In contrast to hamartoma, choristomatous tissue has normal or near normal histologic architecture.

#Clinodactyly: Permanent deflection of one or more finger.

#Cerebro-ocular dysplasia and muscular dystrophy (COD-MD): Agyric disorder combined with malformation of the visual system. This is considered a synonym or an entity similar to Walker-Warburg syndrome.

#Congenital: congenital malformations and structural abnormalities refer to growth disorders with structural defects that are present at birth.

#Coloboma: An apparent absence or defect of some ocular tissue, usually due to failure of a part of the fetal tissue to close; it may affect the choroid, ciliary body, eyelids, iris, lens, optic nerve, or retina.

#Colpocephaly: Refers to the disproportionate enlargement of the occipital horns; the anterior horns of the lateral ventricles are also usually enlarged in cerebral malformations. Because the primary fault is failure of growth of the cerebral mantle and because the term "colpocephaly" has been used for a heterogenous group of cases, it should not be used.

#Cortical dysplasia: Cortical dysplasia is characterized by the presence of abnormal neurons and glia arranged abnormally in focal areas of the cerebral cortex. The separation between cortical dyplasia and microscopic migration disorder is arbitary, if it exists.

#Cortical lamination: Variations of abnormal cortical lamination, often associated with polymicrogyria and pachygyria are as follows:

·         Unlayered cortex: There is a molecular layer and a single band of unlayered neurons.

·         Four layered cortex: There is a molecular layer, then a layer of unlaminated neurons arranged in a sinus band like the tracing of a sound wave, then a straight horizontal cell-poor layer, which in older individuals usualy contains myelin, beneath which there is another straight hroizontal layer of unlaminated neurons.

·         Parallel four-layered cortex: This has the same four layers as the previously decribed cortex with all layers paralleling each other.

·         Miniature gyri: Miniature gyri are fused so that the molecular layer of adjacent gyri abut each other, with the line of fusion being marked by prominent vessels.

·         Poorly laminated: Four layers may not always be evident.

#Cranioarachischisis: (-rachis, Greek, the backbone or the spine) Brain and spinal cord are exposed to the surrounding amniotic fluid, resulting in necrosis, degeneration or angioma-like formations. The optic system, however, is relatively well developed.  Since the neural tube has multiple simultaneous fusion sites, this phenomenon may be explained by normal fusion of the rostral portion of the neural tube leading to a normal prosencephalon but non-fusion of the caudal part of the neural tube.

#Cranioectomesodermal hypoplasia: The cerebral hemispheres are covered by a thin membrane consisted of a single layer of cuboidal epithelium overlying a thin collagenous layer, which in turn overlay another cuboidal epithelium that covered the cerebral hemispheres. The skull base, orbits, and facial bones were normal. In contrast to anencephaly, there is no clavarial bone. The clivus represents the most dorsal and cephalad bony structure.

#Cyclopia: A developmental anomaly characterized by a single orbital fossa, with the globe absent or rudimentary, apparently normal, or dulplicated, or the nose absent or present as a tubular appendix located above the orbit.

 

Syndromes and SequencesHead

#Cerebro-ocular dysplasia: A family of syndromes characterized by cerebral cortical dysplasia and ocular abnormalities. Muscular disorder is also common. They are better known as cerebro-ocular-muscular disease.

#Cerebro-ocular-muscular Syndrome (COD-MD): Similar to Warburg-Walker syndrome with the addition rising creatine phosphokinase and electromyographic evidence of myopathy.

#Caudal Regression Syndrome (sacral agenesis): The caudal regression syndrome is a variable defect of lumbar vertebrae, sacrum, and coccyx. This is a severe developmental field defect of the posterior axis caudal blastema. The severest form is sirenomelia (mermaid syndrome). It is frequently associated with abnormalities of the anorectal and urogenital systems and lower limbs. The entire urinary tract can be absent. The pathogenesis is probably related to the failure of growth of the caudal eminence. The strongest association of caudal regression is with maternal diabetes, it has also been related to deletion of chromosome 7q, autosomal dominant and, probably, autosomal recessive transmission. Timing: it occurs in the primitive streak stage during week 3 of gestation before development of the allantois, and the allantoic vessels are usually absent. There is a single umbilical artery that arises directly from the aorta.

·         Type I: total or partial sacral agenesis and is characterized by unilateral sacral agenesis.

·         Type II: partial agenesis of the sacrum, a normal or hypoplastic first sacral vertebra, and a stable sacroiliac joint. This is the most frequent type.

·         Type III: total sacral agenesis and variable lumbar agenesis, and the ilia articulate with the lowest vertebra present.

·         Type IV: total sacral agenesis and variable lumbar agenesis, and the caudal end-plate of the lowest vertebra rests above either the fused iliac wings or there is an iliac amphiarthrosis.

·         Currarino triad: the combination of sacral agenesis with a presacral mass, which can include a teratoma or anterior sacral meningocele, and anorectal stenosis. Development of teratoma can be explained by the multipotential cells of the tail bud.

#Contiguous gene syndromes: it refers to a group of disorders characterized by subtle cytogenetif deletions detectable by high-resolution chromosome analysis. The recognizable phenotypes of these syndromes most likely result from deletion of several functionally unrelated genes that are physically contiguous on a chromosome. Clinical variation within these syndromes may be related to different sizes of the deletions.

#Coffin-Siris syndrome: This is an ectomesodermal syndrome. Dandy-Walker hindbrain, hypertrichosis, hypotonia, lax joints, abnormal facies, and developmental delay,

NeuroLearn NeuroHelp Malformations General Syndromes For Comment: KarMing-Fung@ouhsc.edu